Bilateral Temporomandibular Joint Ankylosis with Rare Finding of Odontogenic Keratocyst Extending into Ankylosed Segment: An Anomaly within Anomaly


  • Government College of Dentistry, Indore, Department of Oral and Maxillofacial Surgery, Madhya Pradesh, 452001, India


Temporomandibular joint ankylosis is a pathological condition where the mandible fused to the glenoid fossa by bony and fibrotic tissues, which leads to a restriction of the mouth opening from partial reduction to complete immobility of the jaw. It is most commonly associated with trauma followed by local or systemic infection, tumors or systemic disease such as ankylosing spondylitis, rheumatoid arthritis, or psoriasis. This is a case report of an unusual presentation of bilateral Temporomandibular Joint (TMJ) ankylosis with rare finding of odontogenic keratocyst extending into the ankylosed segment. The CT scan revealed a welldefined with multicystic radiolucency appearance replaced the usual picture of TMJ ankylosis of a radio-opaque mass obliterating the normal architecture of the joint. Surgical exploration revealed cystic cavity filled with cheesy material within the ankylosed mass on right side of TMJ.


Temporomandibular Joint, Odontogenic Keratocyst, Keratocystic Odontogenic Tumor

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